We encountered a rare course of superficial branch of radial nerve (SBRN) on the left upper extremity of a 36 years old male cadaver during routine dissection in the Anatomy Laboratory. Insert tendon of brachioradial muscle was two parts and SBRN was passing between two slips of tendon. Courses and locations of the other anatomical structures were normal. It was thought that SBRN had been compressed during movements of brachioradial muscle because of its abnormal course. This anatomical variation was assessed as “Wartenberg’s Syndrome” characterized by pain, paresthesia and absence of sense on radial side of dorsum of hand, wrist and forearm. Importance of the region anatomy was stressed for clinical evaluations and surgical approaches to this rarely syndrome. ©2008, Firat University, Medical Faculty